[en] The presence of atherosclerotic plaque vessels is a critical factor in plaque destabilization. This may be attributable to the leaky phenotype of these microvessels, although direct proof for this notion is lacking. In this study, we investigated molecular and cellular patterns of stable and hemorrhaged human plaque to identify novel drivers of intraplaque vessel dysfunction. From transcriptome data of a human atherosclerotic lesion cohort, we reconstructed a co-expression network, identifying a gene module strongly and selectively correlated with both plaque microvascular density and inflammation. Spectrin Beta Non-Erythrocytic 1 (sptbn1) was identified as one of the central hubs of this module (along with zeb1 and dock1) and was selected for further study based on its predominant endothelial expression. Silencing of sptbn1 enhanced leukocyte transmigration and vascular permeability in vitro, characterized by an increased number of focal adhesions and reduced junctional VE-cadherin. In vivo, sptbn1 knockdown in zebrafish impaired the development of the caudal vein plexus. Mechanistically, increased substrate stiffness was associated with sptbn1 downregulation in endothelial cells in vitro and in human vessels. Plaque SPTBN1 mRNA and protein expression were found to correlate with an enhanced presence of intraplaque hemorrhage and future cardiovascular disease (CVD) events during follow-up. In conclusion, we identify SPTBN1 as a central hub gene in a gene program correlating with plaque vascularisation. SPTBN1 was regulated by substrate stiffness in vitro while silencing blocked vascular development in vivo, and compromised barrier function in vitro. Together, SPTBN1 is identified as a new potential regulator of the leaky phenotype of atherosclerotic plaque microvessels.
Disciplines :
Biochemistry, biophysics & molecular biology
Author, co-author :
Rademakers, Timo; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands ; Department of Plasma Proteins, Laboratory for Molecular Cell Biology, Sanquin Research and Landsteiner Laboratory, Amsterdam, The Netherlands
Manca, Marco; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Jin, Han; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Orban, Tanguy; Laboratory of Protein Signaling and Interactions, GIGA, Liège Université, Liège, Belgium
Perisic, Ljubica Matic; Division of Vascular Surgery, Department of Molecular Medicine and Surgery, Karolinska Institutet and Karolinska Hospital, Stockholm, Sweden
Frissen, Hubertus J M; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Rühle, Frank; Genetic Epidemiology, Institute of Human Genetics, University of Münster, Münster, Germany
Hautvast, Petra; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
van Rijssel, Jos; Department of Plasma Proteins, Laboratory for Molecular Cell Biology, Sanquin Research and Landsteiner Laboratory, Amsterdam, The Netherlands
van Kuijk, Kim; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Mees, Barend M E; Department of Vascular Surgery, Maastricht University Medical Center, Maastricht, The Netherlands
Peutz-Kootstra, Carine J; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Heeneman, Sylvia; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands
Daemen, Mat J A P; Department of Pathology, Academic Medical Center (AMC), Amsterdam, The Netherlands
Pasterkamp, Gerard; Laboratory of Clinical Chemistry and Haematology, University Medical Center Utrecht, University of Utrecht, Utrecht, The Netherlands
Stoll, Monika; Genetic Epidemiology, Institute of Human Genetics, University of Münster, Münster, Germany ; Maastricht Center for Systems Biology (MaCSBio, Cardiovascular Research Institute Maastricht (CARIM), Maastricht, The Netherlands ; Department of Biochemistry, Maastricht University, Maastricht, The Netherlands
van Zandvoort, Marc A M J; Department of Molecular Cell Biology, Cardiovascular Research Institute Maastricht (CARIM), Maastricht University, Maastricht, The Netherlands
Hedin, Ulf; Division of Vascular Surgery, Department of Molecular Medicine and Surgery, Karolinska Institutet and Karolinska Hospital, Stockholm, Sweden
Dequiedt, Franck ; Université de Liège - ULiège > Département des sciences de la vie > Génétique et biologie moléculaires animales
van Buul, Jaap D; Department of Plasma Proteins, Laboratory for Molecular Cell Biology, Sanquin Research and Landsteiner Laboratory, Amsterdam, The Netherlands
Sluimer, Judith C; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands ; Centre for Cardiovascular Science, University of Edinburgh, Edinburgh, UK ; Department for Renal and Hypertensive, Rheumatological and Immunological Diseases (Medical Clinic II), RWTH Aachen, Aachen, Germany
Biessen, Erik A L; Department of Pathology, Experimental Vascular Pathology Group, Maastricht University, PO box 5800, 6202 AZ, Maastricht, The Netherlands. erik.biessen@mumc.nl ; Institute for Molecular Cardiovascular Research, RWTH Aachen, Aachen, Germany. erik.biessen@mumc.nl
This study was supported by the CARIM portfolio excellence program \u201CPlaque neoangiogenesis\u201D (TR, SH, MAMJvZ, EB), the Centre for translational Molecular Medicine (CTMM) project Circulating cells (grant number 01C-102; MM, EB), and the China Scholarship Council (CSC) grant 201609120004 (HJ). The BiKE study (LM, UH) is supported by the Swedish Heart and Lung Foundation; Swedish Research Council (K2009-65X-2233\u201301-3, K2013-65X-06816\u201330-4, 349\u20132007-8703); Uppdrag Besegra Stroke (P581/2011\u2013123); Stockholm County Council (ALF2011-0260, ALF-2011\u20130279). LM is recipient of fellowships and grants from the Swedish Society for Medical Research; Swedish Heart and Lung Foundation, Tore Nilsson\u2019s, Magnus Bergvall\u2019s and Karolinska Institute Foundations.
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